Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001246291 | SCV001419634 | likely pathogenic | X-linked lymphoproliferative disease due to SH2D1A deficiency | 2020-01-31 | criteria provided, single submitter | clinical testing | In summary, the currently available evidence indicates that the variant is pathogenic, but additional data are needed to prove that conclusively. Therefore, this variant has been classified as Likely Pathogenic. Loss-of-function variants in SH2D1A are known to be pathogenic (PMID: 9771704, 11049992, 15711562). This variant has not been reported in the literature in individuals with SH2D1A-related conditions. This variant results in the deletion of part of exon 2 (c.197_201+9del) of the SH2D1A gene. It is expected to disrupt RNA splicing and likely results in an absent or disrupted protein product. |