Total submissions: 8
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Ce |
RCV000997888 | SCV001153643 | pathogenic | not provided | 2024-03-01 | criteria provided, single submitter | clinical testing | MN1: PM6:Strong, PM2, PS4:Moderate, PVS1:Moderate |
SIB Swiss Institute of Bioinformatics | RCV001003397 | SCV001432978 | pathogenic | CEBALID syndrome | 2020-07-29 | criteria provided, single submitter | curation | This variant is interpreted as Pathogenic for CEBALID syndrome, autosomal dominant. The following ACMG Tag(s) were applied: Absent from controls (or at extremely low frequency if recessive) in Exome Sequencing Project, 1000 Genomes Project, or Exome Aggregation Consortium (PM2); Protein length changes as a result of in-frame deletions/insertions in a nonrepeat region or stop-loss variants (PM4); De novo (paternity and maternity confirmed) (PS2 upgraded to very strong); Prevalence in affected individuals statistically increased over controls (PS4 downgraded to supporting). |
Gene |
RCV000997888 | SCV001989864 | uncertain significance | not provided | 2019-06-04 | criteria provided, single submitter | clinical testing | Variants in candidate genes are classified as variants of uncertain significance in accordance with ACMG guidelines (Richards et al., 2015); Not observed in large population cohorts (Lek et al., 2016); Has not been previously published as pathogenic or benign to our knowledge; Nonsense variant predicted to result in protein truncation or nonsense mediated decay in a gene for which loss-of-function is not a known mechanism of disease; This variant is associated with the following publications: (PMID: 31834374) |
Baylor Genetics | RCV001003397 | SCV004040764 | pathogenic | CEBALID syndrome | 2023-06-02 | criteria provided, single submitter | clinical testing | |
OMIM | RCV001003397 | SCV001161684 | pathogenic | CEBALID syndrome | 2020-02-14 | no assertion criteria provided | literature only | |
University of Washington Center for Mendelian Genomics, |
RCV001258027 | SCV001434841 | likely pathogenic | MN1 C-terminal truncation (MCTT) syndrome | no assertion criteria provided | research | ||
Gene |
RCV001003397 | SCV001469063 | not provided | CEBALID syndrome | no assertion provided | literature only | Recurrent pathogenic variant in 3 out of 25 persons | |
Solve- |
RCV004768771 | SCV005091262 | likely pathogenic | Familial meningioma | 2022-06-01 | no assertion criteria provided | provider interpretation | Variant confirmed as disease-causing by referring clinical team |