Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV000007924 | SCV003523292 | uncertain significance | Pyogenic bacterial infections due to MyD88 deficiency | 2022-04-04 | criteria provided, single submitter | clinical testing | This variant is also known as c.586C>T (p.Arg196Cys) and R196C. ClinVar contains an entry for this variant (Variation ID: 7495). This variant is present in population databases (rs137853064, gnomAD 0.006%). This missense change has been observed in individual(s) with clinical features of MyD88 deficiency (PMID: 18669862). It has also been observed to segregate with disease in related individuals. This sequence change replaces arginine, which is basic and polar, with cysteine, which is neutral and slightly polar, at codon 209 of the MYD88 protein (p.Arg209Cys). Algorithms developed to predict the effect of missense changes on protein structure and function (SIFT, PolyPhen-2, Align-GVGD) all suggest that this variant is likely to be disruptive. Experimental studies have shown that this missense change affects MYD88 function (PMID: 18669862, 19506249, 24316379). In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
OMIM | RCV000007924 | SCV000028129 | pathogenic | Pyogenic bacterial infections due to MyD88 deficiency | 2008-08-01 | no assertion criteria provided | literature only |