Total submissions: 5
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV000468446 | SCV000553100 | uncertain significance | Microcephaly, normal intelligence and immunodeficiency | 2023-09-15 | criteria provided, single submitter | clinical testing | In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. An algorithm developed to predict the effect of missense changes on protein structure and function (PolyPhen-2) suggests that this variant is likely to be tolerated. ClinVar contains an entry for this variant (Variation ID: 411778). This missense change has been observed in individual(s) with breast cancer, bone marrow failure and/or myelodysplastic syndrome (PMID: 25239263, 35039564). This variant is not present in population databases (gnomAD no frequency). This sequence change replaces lysine, which is basic and polar, with glutamic acid, which is acidic and polar, at codon 236 of the NBN protein (p.Lys236Glu). |
Ambry Genetics | RCV000569502 | SCV000670277 | uncertain significance | Hereditary cancer-predisposing syndrome | 2024-05-23 | criteria provided, single submitter | clinical testing | The p.K236E variant (also known as c.706A>G), located in coding exon 7 of the NBN gene, results from an A to G substitution at nucleotide position 706. The lysine at codon 236 is replaced by glutamic acid, an amino acid with similar properties. In a study of patients with idiopathic bone marrow failure or myelodysplastic syndrome, this variant was seen in an 18-year-old male with bone marrow failure (Zhang MY et al. Haematologica. 2015 Jan;100:42-8)This amino acid position is well conserved in available vertebrate species. In addition, the in silico prediction for this alteration is inconclusive. Based on the available evidence, the clinical significance of this variant remains unclear. |
Gene |
RCV001575608 | SCV001802640 | uncertain significance | not provided | 2019-06-14 | criteria provided, single submitter | clinical testing | Not observed in large population cohorts (Lek et al., 2016); In silico analysis, which includes protein predictors and evolutionary conservation, supports a deleterious effect; This variant is associated with the following publications: (PMID: 25239263) |
Genome- |
RCV000468446 | SCV002044806 | uncertain significance | Microcephaly, normal intelligence and immunodeficiency | 2021-11-07 | criteria provided, single submitter | clinical testing | |
Sema4, |
RCV000569502 | SCV002536708 | uncertain significance | Hereditary cancer-predisposing syndrome | 2021-09-16 | criteria provided, single submitter | curation |