Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Illumina Laboratory Services, |
RCV003985152 | SCV004801447 | likely pathogenic | Hyperphosphatasemia with bone disease | 2019-01-29 | criteria provided, single submitter | clinical testing | The TNFRSF11B c.419_420delCA p.(Thr140SerfsTer13) variant causes a shift in the protein reading frame that is predicted to result in premature termination of the protein. Loss of normal protein function through either protein truncation or nonsense-mediated mRNA decay is expected. To our knowledge, this variant has not been reported in the peer-reviewed literature. This variant is reported at a frequency of 0.000009 in the European (non-Finnish) population of the Genome Aggregation Database (version 2.1.1); however, this frequency is based on one allele only in a region of good sequencing coverage. Based on the available evidence, the c.419_420delCA p.(Thr140SerfsTer13) variant is classified as likely pathogenic for juvenile Paget disease. |