Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV000556121 | SCV000630707 | uncertain significance | Gastrointestinal stromal tumor; Paragangliomas 4; Pheochromocytoma | 2021-09-01 | criteria provided, single submitter | clinical testing | This sequence change replaces phenylalanine with valine at codon 146 of the SDHB protein (p.Phe146Val). The phenylalanine residue is highly conserved and there is a small physicochemical difference between phenylalanine and valine. This variant is not present in population databases (ExAC no frequency). This missense change has been observed in individual(s) with pheochromocytoma (PMID: 30877234). ClinVar contains an entry for this variant (Variation ID: 459147). Advanced modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) performed at Invitae indicates that this missense variant is expected to disrupt SDHB protein function. In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
Ambry Genetics | RCV001022374 | SCV001184103 | uncertain significance | Hereditary cancer-predisposing syndrome | 2023-12-07 | criteria provided, single submitter | clinical testing | The p.F146V variant (also known as c.436T>G), located in coding exon 5 of the SDHB gene, results from a T to G substitution at nucleotide position 436. The phenylalanine at codon 146 is replaced by valine, an amino acid with highly similar properties. This amino acid position is highly conserved in available vertebrate species. In addition, this alteration is predicted to be deleterious by in silico analysis. Since supporting evidence is limited at this time, the clinical significance of this alteration remains unclear. |
Gene |
RCV004721418 | SCV005328013 | uncertain significance | not provided | 2024-03-18 | criteria provided, single submitter | clinical testing | Identified in a patient with a single pheochromocytoma (PCC) in published literature (PMID: 30877234); Not observed at significant frequency in large population cohorts (gnomAD); In silico analysis supports that this missense variant has a deleterious effect on protein structure/function; This variant is associated with the following publications: (PMID: 30877234) |