Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001866448 | SCV002123584 | uncertain significance | Renal carnitine transport defect | 2022-09-01 | criteria provided, single submitter | clinical testing | This sequence change replaces serine, which is neutral and polar, with alanine, which is neutral and non-polar, at codon 39 of the SLC22A5 protein (p.Ser39Ala). This variant is present in population databases (rs544332057, gnomAD 0.03%). This variant has not been reported in the literature in individuals affected with SLC22A5-related conditions. ClinVar contains an entry for this variant (Variation ID: 1354484). Advanced modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) performed at Invitae indicates that this missense variant is not expected to disrupt SLC22A5 protein function. In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
Giacomini Lab, |
RCV001866448 | SCV002576597 | likely benign | Renal carnitine transport defect | 2022-10-03 | criteria provided, single submitter | research | |
Revvity Omics, |
RCV001866448 | SCV003823355 | uncertain significance | Renal carnitine transport defect | 2019-11-25 | criteria provided, single submitter | clinical testing | |
Ambry Genetics | RCV003164065 | SCV003879835 | uncertain significance | Inborn genetic diseases | 2023-03-07 | criteria provided, single submitter | clinical testing | The c.115T>G (p.S39A) alteration is located in exon 1 (coding exon 1) of the SLC22A5 gene. This alteration results from a T to G substitution at nucleotide position 115, causing the serine (S) at amino acid position 39 to be replaced by an alanine (A). Based on insufficient or conflicting evidence, the clinical significance of this alteration remains unclear. |