Total submissions: 6
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV000698844 | SCV000827533 | pathogenic | Renal carnitine transport defect | 2024-02-02 | criteria provided, single submitter | clinical testing | This sequence change replaces glutamine, which is neutral and polar, with glutamic acid, which is acidic and polar, at codon 180 of the SLC22A5 protein (p.Gln180Glu). This variant is present in population databases (no rsID available, gnomAD 0.006%). This missense change has been observed in individual(s) with primary carnitine deficiency (PMID: 32371215, 33181153). ClinVar contains an entry for this variant (Variation ID: 576364). Advanced modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) performed at Invitae indicates that this missense variant is expected to disrupt SLC22A5 protein function with a positive predictive value of 95%. For these reasons, this variant has been classified as Pathogenic. |
Myriad Genetics, |
RCV000698844 | SCV002060014 | uncertain significance | Renal carnitine transport defect | 2021-11-11 | criteria provided, single submitter | clinical testing | NM_003060.3(SLC22A5):c.538C>G(Q180E) is a missense variant classified as a variant of uncertain significance in the context of primary carnitine deficiency. Q180E has been observed in cases with relevant disease (PMID: 32371215, 33181153). Functional assessments of this variant are not available in the literature. Q180E has been observed in population frequency databases (gnomAD: EAS 0.006%). In summary, there is insufficient evidence to classify NM_003060.3(SLC22A5):c.538C>G(Q180E) as pathogenic or benign. Please note: this variant was assessed in the context of healthy population screening. |
Giacomini Lab, |
RCV000698844 | SCV002576646 | uncertain significance | Renal carnitine transport defect | 2022-10-03 | criteria provided, single submitter | research | |
Baylor Genetics | RCV000698844 | SCV004201290 | likely pathogenic | Renal carnitine transport defect | 2023-12-30 | criteria provided, single submitter | clinical testing | |
Fulgent Genetics, |
RCV000698844 | SCV005669202 | likely pathogenic | Renal carnitine transport defect | 2024-06-04 | criteria provided, single submitter | clinical testing | |
Natera, |
RCV001274334 | SCV001458330 | uncertain significance | Decreased circulating carnitine concentration | 2020-03-17 | no assertion criteria provided | clinical testing |