Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
3billion, |
RCV003152856 | SCV003841321 | likely pathogenic | Intellectual disability, autosomal dominant 16 | 2023-02-23 | criteria provided, single submitter | clinical testing | The variant is not observed in the gnomAD v2.1.1 dataset. Missense changes are a common disease-causing mechanism. In silico tool predictions suggest damaging effect of the variant on gene or gene product (REVEL: 0.60; 3Cnet: 0.50). The variant has been previously reported as assumed (i.e. paternity and maternity not confirmed) de novo in at least one similarly affected unrelated individual (PMID: 29095814). A different missense change at the same codon (p.Arg451Cys) has been reported as pathogenic/likely pathogenic with strong evidence (ClinVar ID: VCV000937431). Therefore, this variant is classified as Likely pathogenic according to the recommendation of ACMG/AMP guideline. |