Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Genetic Services Laboratory, |
RCV000500325 | SCV000597195 | uncertain significance | not specified | 2015-09-24 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV002524299 | SCV003346275 | likely pathogenic | Rhabdoid tumor predisposition syndrome 2 | 2022-05-31 | criteria provided, single submitter | clinical testing | In summary, the currently available evidence indicates that the variant is pathogenic, but additional data are needed to prove that conclusively. Therefore, this variant has been classified as Likely Pathogenic. Algorithms developed to predict the effect of missense changes on protein structure and function (SIFT, PolyPhen-2, Align-GVGD) all suggest that this variant is likely to be disruptive. ClinVar contains an entry for this variant (Variation ID: 436811). This missense change has been observed in individual(s) with Coffin-Siris syndrome (Invitae). In at least one individual the variant was observed to be de novo. This variant is not present in population databases (gnomAD no frequency). This sequence change replaces proline, which is neutral and non-polar, with arginine, which is basic and polar, at codon 946 of the SMARCA4 protein (p.Pro946Arg). |