Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
New York Genome Center | RCV001291810 | SCV001480431 | uncertain significance | Intellectual disability, autosomal dominant 27 | 2020-05-26 | criteria provided, single submitter | clinical testing | The c.538G>A (p.Ala180Thr) variant identified in the SOX11 gene of this individual substitutes a moderately conserved Alanine for Threonine at amino acid 180/442 (coding exon 1/1). This variant is found with low frequency in gnomAD(v3.0) (3 heterozygotes, 0 homozygotes; allele frequency: 2.11e-5) suggesting it is not a common benign variant in the populations represented in this database. In silico algorithms predict this variant to be Neutral (Provean; score:-0.48) and Tolerated (SIFT; score:0.401) to the function of the canonical transcript. The p.Ala180 residue is not within a mapped domain of SOX11 (UniProtKB: P35716). Given the lack of compelling evidence for its pathogenicity, the c.538G>A (p.Ala180Thr) variant identified in the SOX11 gene is reported here as a Variant of Uncertain Significance. |