Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Undiagnosed Diseases Network, |
RCV000625997 | SCV000746603 | pathogenic | Hereditary spastic paraplegia 7 | 2017-05-08 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV000625997 | SCV001216339 | likely pathogenic | Hereditary spastic paraplegia 7 | 2023-01-23 | criteria provided, single submitter | clinical testing | In summary, the currently available evidence indicates that the variant is pathogenic, but additional data are needed to prove that conclusively. Therefore, this variant has been classified as Likely Pathogenic. ClinVar contains an entry for this variant (Variation ID: 522825). This frameshift has been observed in individual(s) with clinical features of hereditary spastic paraplegia (PMID: 27557734; Invitae). In at least one individual the data is consistent with being in trans (on the opposite chromosome) from a pathogenic variant. This variant is not present in population databases (gnomAD no frequency). This sequence change results in a frameshift in the SPG7 gene (p.Met757Ilefs*66). While this is not anticipated to result in nonsense mediated decay, it is expected to disrupt the last 39 amino acid(s) of the SPG7 protein and extend the protein by 26 additional amino acid residues. |