Total submissions: 7
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Institute of Medical Genetics and Applied Genomics, |
RCV001268036 | SCV001446629 | pathogenic | not provided | 2020-10-23 | criteria provided, single submitter | clinical testing | |
Mendelics | RCV001255185 | SCV002519819 | pathogenic | Optic atrophy 13 with retinal and foveal abnormalities | 2022-05-04 | criteria provided, single submitter | clinical testing | |
3billion | RCV001255185 | SCV002521243 | pathogenic | Optic atrophy 13 with retinal and foveal abnormalities | 2022-05-22 | criteria provided, single submitter | clinical testing | The variant is not observed in the gnomAD v2.1.1 dataset. Missense changes are a common disease-causing mechanism. Functional studies provide strong evidence of the variant having a damaging effect on the gene or gene product (PMID:31298765). In silico tool predictions suggest no damaging effect of the variant on gene or gene product (REVEL: 0.24; 3Cnet: 0.14). Same nucleotide change resulting in same amino acid change has been previously reported to be associated with SSBP1 related disorder (ClinVar ID: VCV000977503 / PMID: 31298765 / 3billion dataset). The variant has been previously reported as assumed (i.e. paternity and maternity not confirmed) de novo in at least one similarly affected unrelated individual (PMID:31298765). Therefore, this variant is classified as pathogenic according to the recommendation of ACMG/AMP guideline. |
Ce |
RCV001268036 | SCV002563981 | pathogenic | not provided | 2021-02-01 | criteria provided, single submitter | clinical testing | |
Institute of Human Genetics, |
RCV001255185 | SCV004244366 | pathogenic | Optic atrophy 13 with retinal and foveal abnormalities | 2024-01-17 | criteria provided, single submitter | clinical testing | Criteria applied: PS4,PS3_MOD,PS2_STR,PM2_SUP,PP1 |
Gene |
RCV001268036 | SCV005328018 | pathogenic | not provided | 2023-07-17 | criteria provided, single submitter | clinical testing | Published functional studies suggest a damaging effect (PMID: 31550240, 31298765); In silico analysis supports that this missense variant has a deleterious effect on protein structure/function; Not observed at significant frequency in large population cohorts (gnomAD); This variant is associated with the following publications: (PMID: 31550237, 35142387, 33671400, 31298765, 31550240, 36993412) |
OMIM | RCV001255185 | SCV001431539 | pathogenic | Optic atrophy 13 with retinal and foveal abnormalities | 2020-09-03 | no assertion criteria provided | literature only |