Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Centre for Mendelian Genomics, |
RCV000415141 | SCV000492994 | uncertain significance | Hypertelorism; Upslanted palpebral fissure; Clinodactyly of the 5th finger; Opacification of the corneal stroma; Bifid nasal tip | 2014-05-14 | criteria provided, single submitter | clinical testing | |
Centre for Mendelian Genomics, |
RCV001196334 | SCV001366932 | uncertain significance | Char syndrome | 2016-01-01 | criteria provided, single submitter | clinical testing | This variant was classified as: Uncertain significance. |
Illumina Laboratory Services, |
RCV001196334 | SCV002540263 | uncertain significance | Char syndrome | 2021-11-19 | criteria provided, single submitter | clinical testing | The TFAP2B c.830C>G (p.Ser277Trp) missense variant results in the substitution of serine at amino acid position 277 with tryptophan. To our knowledge, this variant has not been reported in the peer-reviewed literature. This variant is not found in version 2.1.1 or version 3.1.2 of the Genome Aggregation Database. This variant lies within the basic domain of the transcription factor AP-2 beta protein, which is necessary for DNA binding (Williams et al. 1991). Variants within the basic domain have been associated with disease and shown to alter the protein's DNA binding ability to have a dominant negative effect on transcription factor transactivation in vitro (Satoda et al. 2000; Zhao et al. 2001). Based on the available evidence, the c.830C>G (p.Ser277Trp) variant is classified as a variant of uncertain significance for Char syndrome. |