Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Gene |
RCV004700224 | SCV005202093 | likely pathogenic | not provided | 2023-07-18 | criteria provided, single submitter | clinical testing | Canonical splice site variant in a gene or region of a gene for which loss of function is not a well-established mechanism of disease; Published RNA studies demonstrate that the variant induced the use of a cryptic splice acceptor and resulted in the in-frame insertion of a 30-bp intronic sequence within the kinase domain (Kosaki et al., 2006); Apparently de novo variant in a patient with ShprintzenGoldberg Syndrome and features including arachnodactyly, craniosynostosis, cardiovascular anomalies, pectus excavatum and scoliosis (Kosaki et al., 2006); Not observed at significant frequency in large population cohorts (gnomAD); This variant is associated with the following publications: (PMID: 25525159, 19339519, 16333834) |
OMIM | RCV000013341 | SCV000033588 | pathogenic | Loeys-Dietz syndrome 2 | 2006-01-01 | no assertion criteria provided | literature only |