Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV000015065 | SCV001237270 | likely pathogenic | Warts, hypogammaglobulinemia, infections, and myelokathexis | 2019-03-21 | criteria provided, single submitter | clinical testing | In summary, the currently available evidence indicates that the variant is pathogenic, but additional data are needed to prove that conclusively. Therefore, this variant has been classified as Likely Pathogenic. This variant has been reported to affect CXCR4 protein function (PMID: 16899028). This variant has been observed in several individuals with clinical features of WHIM syndrome (PMID: 12692554, 16899028, Invitae). ClinVar contains an entry for this variant (Variation ID: 14021). This variant is not present in population databases (ExAC no frequency). This sequence change results in a premature translational stop signal in the CXCR4 gene (p.Ser339Cysfs*4). While this is not anticipated to result in nonsense mediated decay, it is expected to disrupt the last 14 amino acids of the CXCR4 protein. |
OMIM | RCV001801238 | SCV000035321 | pathogenic | WHIM syndrome 1 | 2003-05-01 | no assertion criteria provided | literature only |