Total submissions: 1
| Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
|---|---|---|---|---|---|---|---|---|
| Gene |
RCV000288258 | SCV000330010 | pathogenic | not provided | 2016-02-20 | criteria provided, single submitter | clinical testing | The c.401-3A>G pathogenic variant in the KMT2D gene, denoted as c.400-3A>G due to alternative nomenclature, has been reported previously as a de novo variant in an individual with a clinical diagnosis of Kabuki syndrome (Micale et al., 2011). This variant is predicted to destroy the natural splice acceptor site in intron 3 and create a cryptic splice acceptor site upstream, thus is expected to cause abnormal gene splicing. The c.401-3A>G variant was not observed in approximately 6,100 individuals of European and African American ancestry in the NHLBI Exome Sequencing Project, indicating it is not a common benign variant in these populations. We interpret c.401-3A>G as a pathogenic variant. |