Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Genetic Services Laboratory, |
RCV000147298 | SCV000194671 | pathogenic | Iron accumulation in brain | 2013-02-08 | criteria provided, single submitter | clinical testing | |
Gene |
RCV002253241 | SCV002525380 | uncertain significance | not provided | 2022-05-24 | criteria provided, single submitter | clinical testing | Observed with a second PLA2G6 variant, phase unknown, in an individual with infantile neuroaxonal dystrophy with brain iron in the published literature (Morgan et al., 2006); Not observed at significant frequency in large population cohorts (gnomAD); In silico analysis supports that this missense variant does not alter protein structure/function; This variant is associated with the following publications: (PMID: 26828213, 16783378, 30363890, 31540697) |
Broad Center for Mendelian Genomics, |
RCV002514836 | SCV003760981 | uncertain significance | PLA2G6-associated neurodegeneration | 2023-01-24 | criteria provided, single submitter | curation | The p.Glu567Lys variant in PLA2G6 has been reported in 1 individual, in the compound heterozygous state, with PLA2G6-associated neurodegeneration (PMID: 16783378), and has been identified in 0.009% (3/34590) of Latino/Admixed American chromosomes by the Genome Aggregation Database (gnomAD, http://gnomad.broadinstitute.org; dbSNP ID: rs587784337). Although this variant has been seen in the general population in a heterozygous state, its frequency is low enough to be consistent with a recessive carrier frequency. This variant has also been reported in ClinVar (Variation ID#: 159743) and has been interpreted as pathogenic by Genetic Services Laboratory (University of Chicago). Computational prediction tools and conservation analyses do not provide strong support for or against an impact to the protein In summary, the clinical significance of the p.Glu567Lys variant is uncertain. ACMG/AMP Criteria applied: PM2_supporting (Richards 2015). |