Total submissions: 6
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV002534609 | SCV000936308 | uncertain significance | not provided | 2022-08-16 | criteria provided, single submitter | clinical testing | This sequence change replaces asparagine, which is neutral and polar, with histidine, which is basic and polar, at codon 437 of the IKBKAP protein (p.Asn437His). This variant is present in population databases (rs148609833, gnomAD 0.1%). This variant has not been reported in the literature in individuals affected with IKBKAP-related conditions. ClinVar contains an entry for this variant (Variation ID: 643142). Algorithms developed to predict the effect of missense changes on protein structure and function are either unavailable or do not agree on the potential impact of this missense change (SIFT: "Tolerated"; PolyPhen-2: "Probably Damaging"; Align-GVGD: "Class C0"). In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
Genome- |
RCV000796780 | SCV001786886 | uncertain significance | Familial dysautonomia | 2021-07-14 | criteria provided, single submitter | clinical testing | |
Ambry Genetics | RCV004027574 | SCV002755470 | uncertain significance | not specified | 2023-07-05 | criteria provided, single submitter | clinical testing | The c.1309A>C (p.N437H) alteration is located in exon 12 (coding exon 11) of the IKBKAP gene. This alteration results from a A to C substitution at nucleotide position 1309, causing the asparagine (N) at amino acid position 437 to be replaced by a histidine (H). Based on insufficient or conflicting evidence, the clinical significance of this alteration remains unclear. |
Fulgent Genetics, |
RCV002495051 | SCV002790957 | uncertain significance | Medulloblastoma; Familial dysautonomia | 2022-02-01 | criteria provided, single submitter | clinical testing | |
Breakthrough Genomics, |
RCV002534609 | SCV005195521 | uncertain significance | not provided | criteria provided, single submitter | not provided | ||
Natera, |
RCV000796780 | SCV001462242 | uncertain significance | Familial dysautonomia | 2020-01-17 | no assertion criteria provided | clinical testing |