Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Invitae | RCV001358791 | SCV000933751 | uncertain significance | not provided | 2022-02-24 | criteria provided, single submitter | clinical testing | This sequence change replaces leucine, which is neutral and non-polar, with arginine, which is basic and polar, at codon 748 of the IKBKAP protein (p.Leu748Arg). This variant is present in population databases (no rsID available, gnomAD 0.03%). This variant has not been reported in the literature in individuals affected with IKBKAP-related conditions. ClinVar contains an entry for this variant (Variation ID: 641171). Algorithms developed to predict the effect of missense changes on protein structure and function are either unavailable or do not agree on the potential impact of this missense change (SIFT: "Tolerated"; PolyPhen-2: "Probably Damaging"; Align-GVGD: "Class C0"). In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
Ambry Genetics | RCV004027484 | SCV002755506 | uncertain significance | not specified | 2021-03-29 | criteria provided, single submitter | clinical testing | The p.L748R variant (also known as c.2243T>G), located in coding exon 20 of the IKBKAP gene, results from a T to G substitution at nucleotide position 2243. The leucine at codon 748 is replaced by arginine, an amino acid with dissimilar properties. This amino acid position is highly conserved in available vertebrate species. In addition, the in silico prediction for this alteration is inconclusive. Since supporting evidence is limited at this time, the clinical significance of this alteration remains unclear. |
Fulgent Genetics, |
RCV002487659 | SCV002789295 | uncertain significance | Medulloblastoma; Familial dysautonomia | 2021-12-02 | criteria provided, single submitter | clinical testing | |
Natera, |
RCV000794350 | SCV001457907 | uncertain significance | Familial dysautonomia | 2020-09-16 | no assertion criteria provided | clinical testing |