Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV002008204 | SCV002268156 | uncertain significance | Hermansky-Pudlak syndrome 2 | 2021-10-20 | criteria provided, single submitter | clinical testing | This sequence change replaces glutamic acid with leucine at codon 708 of the AP3B1 protein (p.Glu708Leu). The glutamic acid residue is weakly conserved and there is a @moderate physicochemical difference between glutamic acid and leucine. The frequency data for this variant in the population databases is not available, as this variant may be reported as separate entries in the ExAC database. This variant has not been reported in the literature in individuals affected with AP3B1-related conditions. Algorithms developed to predict the effect of missense changes on protein structure and function are either unavailable or do not agree on the potential impact of this missense change (SIFT: "Not Available"; PolyPhen-2: "Possibly Damaging"; Align-GVGD: "Not Available"). In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |