Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Elsea Laboratory, |
RCV001250052 | SCV001424204 | uncertain significance | Hyperprolinemia type 2 | 2020-04-01 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV001250052 | SCV002166191 | uncertain significance | Hyperprolinemia type 2 | 2022-07-28 | criteria provided, single submitter | clinical testing | This sequence change replaces valine, which is neutral and non-polar, with methionine, which is neutral and non-polar, at codon 67 of the ALDH4A1 protein (p.Val67Met). This variant is present in population databases (rs141327098, gnomAD 0.2%). This variant has not been reported in the literature in individuals affected with ALDH4A1-related conditions. ClinVar contains an entry for this variant (Variation ID: 973437). Algorithms developed to predict the effect of missense changes on protein structure and function are either unavailable or do not agree on the potential impact of this missense change (SIFT: "Deleterious"; PolyPhen-2: "Probably Damaging"; Align-GVGD: "Class C0"). In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
Women's Health and Genetics/Laboratory Corporation of America, |
RCV003987814 | SCV004803700 | uncertain significance | not specified | 2024-01-23 | criteria provided, single submitter | clinical testing | Variant summary: ALDH4A1 c.199G>A (p.Val67Met) results in a conservative amino acid change in the encoded protein sequence. Three of five in-silico tools predict a benign effect of the variant on protein function. The variant allele was found at a frequency of 0.00018 in 1552904 control chromosomes, predominantly at a frequency of 0.0017 within the African or African-American subpopulation in the gnomAD database, including 1 homozygote. c.199G>A has been reported in the literature as a VUS in at least one individual affected with epilepsy without evidence for causality (e.g. Won_2020). These report(s) do not provide unequivocal conclusions about association of the variant with Deficiency of pyrroline-5-carboxylate reductase. To our knowledge, no experimental evidence demonstrating an impact on protein function has been reported. The following publication has been ascertained in the context of this evaluation (PMID: 32695065). ClinVar contains an entry for this variant (Variation ID: 973437). Based on the evidence outlined above, the variant was classified as uncertain significance. |