Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001303299 | SCV001492540 | uncertain significance | Hyperprolinemia type 2 | 2021-09-01 | criteria provided, single submitter | clinical testing | This sequence change replaces arginine with glutamine at codon 113 of the ALDH4A1 protein (p.Arg113Gln). The arginine residue is moderately conserved and there is a small physicochemical difference between arginine and glutamine. This variant is present in population databases (rs371321697, ExAC 0.03%). This variant has not been reported in the literature in individuals affected with ALDH4A1-related conditions. Algorithms developed to predict the effect of missense changes on protein structure and function (SIFT, PolyPhen-2, Align-GVGD) all suggest that this variant is likely to be tolerated. Algorithms developed to predict the effect of sequence changes on RNA splicing suggest that this variant may create or strengthen a splice site. In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
Centre de Biologie Pathologie Génétique, |
RCV001252134 | SCV001427884 | likely benign | Intellectual disability | 2019-01-01 | no assertion criteria provided | clinical testing |