Total submissions: 5
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Athena Diagnostics | RCV000713246 | SCV000843834 | uncertain significance | not provided | 2017-11-03 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV001340319 | SCV001534120 | uncertain significance | Myoclonic dystonia 11 | 2023-08-28 | criteria provided, single submitter | clinical testing | ClinVar contains an entry for this variant (Variation ID: 586563). In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. This premature translational stop signal has been observed in individual(s) with dystonia (PMID: 26046366, 31186545). This variant is present in population databases (rs201378067, gnomAD 0.1%), and has an allele count higher than expected for a pathogenic variant. This sequence change creates a premature translational stop signal (p.Trp7*) in the SGCE gene. However, it is currently unclear if variants that occur in this region of the gene cause disease. |
Gene |
RCV000713246 | SCV001777880 | likely pathogenic | not provided | 2024-09-18 | criteria provided, single submitter | clinical testing | Identified in patients with features of SGCE-related dystonia in published literature (PMID: 26046366, 31186545); Nonsense variant predicted to result in protein truncation or nonsense mediated decay in a gene for which loss of function is a known mechanism of disease; This variant is associated with the following publications: (PMID: 31980526, 31186545, 37688281, 26046366) |
Revvity Omics, |
RCV001340319 | SCV002021230 | pathogenic | Myoclonic dystonia 11 | 2022-11-03 | criteria provided, single submitter | clinical testing | |
Pittsburgh Clinical Genomics Laboratory, |
RCV001340319 | SCV005397774 | likely pathogenic | Myoclonic dystonia 11 | 2024-04-15 | criteria provided, single submitter | clinical testing | This sequence variant is a single nucleotide substitution (G>A) at coding position 21 of the SGCE gene that changes Trp7 to an early termination codon. As it occurs in exon 1 of 11, this variant is predicted to generate a non-functional allele through either the expression of a truncated protein or a loss of sarcoglycan epsilon expression due to nonsense mediated decay. This is a previously reported variant (ClinVar 586563) that has been observed in individuals affected by myoclonus-dystonia (PMID: 37688281, 31186545, 26046366, 31449710). This variant is present in 131 of 1611498 alleles (0.0081%) in the gnomAD v4.0.0 population dataset. Haploinsufficiency in SGCE is a known mechanism of disease. Based upon the evidence, we consider this variant to be likely pathogenic. ACMG Criteria: PS4, PVS1 |