Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Hacettepe Genetic Diseases Diagnosis Center, |
RCV001264761 | SCV001250610 | pathogenic | Acromesomelic dysplasia 1, Maroteaux type | 2020-05-02 | criteria provided, single submitter | clinical testing | Two unrelated patients with typical findings of Acromesomelic dysplasia Maroteaux type were determined to have a homozygous frameshift variant (c.1215delT, p.Gln406SerfsTer23) in NPR2, resulting in a premature stop codon of the protein sequence. The consanguineous parents were heterozygous carriers of this variant. This variant is not present in gnomAD and ExAC databases. This variant was classified as pathogenic based on ACMG variant classification guidelines. |