Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV000630564 | SCV000751529 | uncertain significance | Duchenne muscular dystrophy | 2018-06-06 | criteria provided, single submitter | clinical testing | This sequence change replaces aspartic acid with valine at codon 165 of the DMD protein (p.Asp165Val). The aspartic acid residue is highly conserved and there is a large physicochemical difference between aspartic acid and valine. This variant is not present in population databases (ExAC no frequency). This variant has been reported in individuals affected with Becker muscular dystrophy (PMID: 12632325, Invitae). Experimental studies have shown that this missense change increases protein aggregation and thermal denaturation but does not significantly affect actin-binding affinity (PMID: 20457930). In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
Institute of Human Genetics, |
RCV003388590 | SCV004100325 | pathogenic | Becker muscular dystrophy | no assertion criteria provided | clinical testing |