Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001889199 | SCV002159782 | uncertain significance | not provided | 2022-11-22 | criteria provided, single submitter | clinical testing | Advanced modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) performed at Invitae indicates that this missense variant is not expected to disrupt ECHS1 protein function. ClinVar contains an entry for this variant (Variation ID: 1389349). This variant has not been reported in the literature in individuals affected with ECHS1-related conditions. The frequency data for this variant in the population databases is considered unreliable, as metrics indicate poor data quality at this position in the gnomAD database. This sequence change replaces cysteine, which is neutral and slightly polar, with serine, which is neutral and polar, at codon 21 of the ECHS1 protein (p.Cys21Ser). In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
Revvity Omics, |
RCV003492694 | SCV004234672 | uncertain significance | Mitochondrial short-chain Enoyl-Coa hydratase 1 deficiency | 2023-03-27 | criteria provided, single submitter | clinical testing |