Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Genetic Services Laboratory, |
RCV000501834 | SCV000595322 | uncertain significance | not specified | 2016-08-08 | criteria provided, single submitter | clinical testing | |
Baylor Genetics | RCV001329820 | SCV001521360 | uncertain significance | Syndromic X-linked intellectual disability Claes-Jensen type | 2020-07-09 | criteria provided, single submitter | clinical testing | This variant was determined to be of uncertain significance according to ACMG Guidelines, 2015 [PMID:25741868]. |
Mayo Clinic Laboratories, |
RCV001509121 | SCV001715660 | uncertain significance | not provided | 2019-07-29 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV003750799 | SCV004523088 | uncertain significance | Spastic paraplegia | 2023-08-30 | criteria provided, single submitter | clinical testing | This variant is not present in population databases (gnomAD no frequency). In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. Advanced modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) performed at Invitae indicates that this missense variant is not expected to disrupt KDM5C protein function. ClinVar contains an entry for this variant (Variation ID: 435565). This variant has not been reported in the literature in individuals affected with KDM5C-related conditions. This sequence change replaces asparagine, which is neutral and polar, with lysine, which is basic and polar, at codon 1522 of the KDM5C protein (p.Asn1522Lys). |