Total submissions: 5
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Invitae | RCV000527753 | SCV000631114 | uncertain significance | Baller-Gerold syndrome | 2023-11-08 | criteria provided, single submitter | clinical testing | This sequence change replaces arginine, which is basic and polar, with tryptophan, which is neutral and slightly polar, at codon 902 of the RECQL4 protein (p.Arg902Trp). The frequency data for this variant in the population databases is considered unreliable, as metrics indicate poor data quality at this position in the gnomAD database. This variant has not been reported in the literature in individuals affected with RECQL4-related conditions. ClinVar contains an entry for this variant (Variation ID: 459424). Advanced modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) performed at Invitae indicates that this missense variant is expected to disrupt RECQL4 protein function with a positive predictive value of 80%. In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
Institute for Clinical Genetics, |
RCV003237906 | SCV002009907 | uncertain significance | not provided | 2021-11-03 | criteria provided, single submitter | clinical testing | |
Laboratory of Molecular Epidemiology of Birth Defects, |
RCV003153690 | SCV003843643 | likely pathogenic | Ovarian cancer | 2022-01-01 | criteria provided, single submitter | clinical testing | |
Prevention |
RCV004527637 | SCV004104806 | uncertain significance | RECQL4-related disorder | 2023-01-17 | criteria provided, single submitter | clinical testing | The RECQL4 c.2704C>T variant is predicted to result in the amino acid substitution p.Arg902Trp. This variant was reported in an individual with sporadic breast cancer (Table 2, Moradian et al. 2021. PubMed ID: 33558524). This variant is reported in 0.0011% of alleles in individuals of European (Non-Finnish) descent in gnomAD (http://gnomad.broadinstitute.org/variant/8-145738281-G-A) and is interpreted as a variant of uncertain significance in ClinVar (https://www.ncbi.nlm.nih.gov/clinvar/variation/459424). At this time, the clinical significance of this variant is uncertain due to the absence of conclusive functional and genetic evidence. |
Center of Medical Genetics and Primary Health Care | RCV001269499 | SCV001449048 | uncertain significance | Malignant tumor of breast | no assertion criteria provided | clinical testing |