Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001851120 | SCV002115196 | likely pathogenic | Myofibrillar myopathy 6; Dilated cardiomyopathy 1HH | 2017-06-24 | criteria provided, single submitter | clinical testing | For these reasons, this variant has been classified as Likely Pathogenic. This variant leads to the truncation of the last 127 amino acids of the BAG3 protein. Different variants downstream of this truncation, p.Glu455Lys and Tyr451*, have been reported as being pathogenic (PMID:  (PMID: 2159883, 25008357, 25008357) indicating that this truncated region may be critical for protein function. This variant is not present in population databases (ExAC no frequency) and has not been reported in the literature in individuals with a BAG3-related disease. This sequence change results in a premature translational stop signal in the last exon of the BAG3 mRNA at codon 449 (p.Lys449*). While this is not anticipated to result in nonsense mediated decay, it is expected to create a truncated BAG3 protein. |