Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Blueprint Genetics | RCV000208446 | SCV000263787 | uncertain significance | Primary dilated cardiomyopathy | 2015-09-29 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV000648827 | SCV000770648 | uncertain significance | Myofibrillar myopathy 6; Dilated cardiomyopathy 1HH | 2019-06-11 | criteria provided, single submitter | clinical testing | This variant is present in population databases (rs727502896, ExAC 0.002%). In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. Algorithms developed to predict the effect of missense changes on protein structure and function do not agree on the potential impact of this missense change (SIFT: "Tolerated"; PolyPhen-2: "Probably Damaging"; Align-GVGD: "Class C0"). This variant has not been reported in the literature in individuals with BAG3-related disease. ClinVar contains an entry for this variant (Variation ID: 222509). This sequence change replaces arginine with cysteine at codon 19 of the BAG3 protein (p.Arg19Cys). The arginine residue is weakly conserved and there is a large physicochemical difference between arginine and cysteine. |