Total submissions: 5
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Laboratory for Molecular Medicine, |
RCV000037922 | SCV000061585 | likely pathogenic | Cardio-facio-cutaneous syndrome | 2012-04-13 | criteria provided, single submitter | clinical testing | The Val487Gly variant in BRAF has been identified in one individual with Cardio- Facio-Cutaneous (CFC) syndrome and was absent in 210 Caucasian control chromosom es (Narumi 2007). Valine (Val) at position 487 is highly conserved across evolut ionarily distant species, increasing the likelihood that the change would not be tolerated. Computational analyses (biochemical amino acid properties, conservat ion, AlignGVGD, PolyPhen2 and SIFT) suggest that the Val487Gly variant may impac t the protein, though this information is not predictive enough to determine pat hogenicity. In summary, this variant is likely to be pathogenic, though segregat ion studies and functional analyses are required to fully establish the pathogen icity of this variant. |
Ambry Genetics | RCV000622585 | SCV000740925 | pathogenic | Inborn genetic diseases | 2015-05-29 | criteria provided, single submitter | clinical testing | |
Blueprint Genetics | RCV000788814 | SCV000928070 | pathogenic | not provided | 2018-11-21 | criteria provided, single submitter | clinical testing | |
Gene |
RCV000788814 | SCV002008924 | pathogenic | not provided | 2021-01-19 | criteria provided, single submitter | clinical testing | Not observed in large population cohorts (Lek et al., 2016); Missense variants in this gene are often considered pathogenic (Stenson et al., 2014); In silico analysis supports that this missense variant has a deleterious effect on protein structure/function; This variant is associated with the following publications: (PMID: 26795593, 17366577, 24719372, 18470943, 18413255, 33482860, 24803665) |
Labcorp Genetics |
RCV001852794 | SCV002196994 | pathogenic | RASopathy | 2021-07-21 | criteria provided, single submitter | clinical testing | This variant is not present in population databases (ExAC no frequency). For these reasons, this variant has been classified as Pathogenic. Advanced modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) performed at Invitae indicates that this missense variant is expected to disrupt BRAF protein function. ClinVar contains an entry for this variant (Variation ID: 44806). This variant has been observed in individuals with BRAF-related conditions (PMID: 17366577, 22495831, 24719372, 26795593). This sequence change replaces valine with glycine at codon 487 of the BRAF protein (p.Val487Gly). The valine residue is highly conserved and there is a moderate physicochemical difference between valine and glycine. |