Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Eurofins Ntd Llc |
RCV000346399 | SCV000345928 | uncertain significance | not provided | 2016-09-15 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV001204802 | SCV001376025 | uncertain significance | Bethlem myopathy 1A | 2020-07-31 | criteria provided, single submitter | clinical testing | This sequence change replaces threonine with isoleucine at codon 501 of the COL6A3 protein (p.Thr501Ile). The threonine residue is moderately conserved and there is a moderate physicochemical difference between threonine and isoleucine. This variant is present in population databases (rs776324215, ExAC 0.001%). This variant has not been reported in the literature in individuals with COL6A3-related conditions. ClinVar contains an entry for this variant (Variation ID: 291216). Algorithms developed to predict the effect of missense changes on protein structure and function are either unavailable or do not agree on the potential impact of this missense change (SIFT: "Deleterious"; PolyPhen-2: "Probably Damaging"; Align-GVGD: "Class C15"). In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
Prevention |
RCV004549630 | SCV004110765 | uncertain significance | COL6A3-related disorder | 2023-04-17 | criteria provided, single submitter | clinical testing | The COL6A3 c.1502C>T variant is predicted to result in the amino acid substitution p.Thr501Ile. To our knowledge, this variant has not been reported in the literature. This variant is reported in 0.0018% of alleles in individuals of European (Non-Finnish) descent in gnomAD (http://gnomad.broadinstitute.org/variant/2-238289953-G-A). At this time, the clinical significance of this variant is uncertain due to the absence of conclusive functional and genetic evidence. |