Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Genetic Services Laboratory, |
RCV000145784 | SCV000192921 | pathogenic | Rubinstein-Taybi syndrome due to CREBBP mutations | 2013-02-08 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV005089681 | SCV005763545 | pathogenic | Rubinstein-Taybi syndrome | 2024-08-20 | criteria provided, single submitter | clinical testing | This sequence change creates a premature translational stop signal (p.Ser318*) in the CREBBP gene. It is expected to result in an absent or disrupted protein product. Loss-of-function variants in CREBBP are known to be pathogenic (PMID: 17052327, 18792986). This variant is not present in population databases (gnomAD no frequency). This variant has not been reported in the literature in individuals affected with CREBBP-related conditions. ClinVar contains an entry for this variant (Variation ID: 158403). For these reasons, this variant has been classified as Pathogenic. |