Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001857671 | SCV002270367 | uncertain significance | Autosomal recessive limb-girdle muscular dystrophy type 2P; Muscular dystrophy-dystroglycanopathy (congenital with brain and eye anomalies), type A9 | 2022-09-03 | criteria provided, single submitter | clinical testing | This sequence change replaces valine, which is neutral and non-polar, with isoleucine, which is neutral and non-polar, at codon 74 of the DAG1 protein (p.Val74Ile). This variant is present in population databases (rs189360006, gnomAD 0.1%). This missense change has been observed in individual(s) with clinical features of muscular dystrophy-dystroglycanopathy (PMID: 25503980). ClinVar contains an entry for this variant (Variation ID: 208540). Algorithms developed to predict the effect of missense changes on protein structure and function output the following: SIFT: "Tolerated"; PolyPhen-2: "Benign"; Align-GVGD: "Class C0". The isoleucine amino acid residue is found in multiple mammalian species, which suggests that this missense change does not adversely affect protein function. Experimental studies have shown that this missense change affects DAG1 function (PMID: 25503980). In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
Revvity Omics, |
RCV003144154 | SCV003830417 | uncertain significance | not provided | 2021-09-15 | criteria provided, single submitter | clinical testing | |
OMIM | RCV000190545 | SCV000245426 | pathogenic | Autosomal recessive limb-girdle muscular dystrophy type 2P | 2015-01-20 | no assertion criteria provided | literature only |