Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Laboratory for Molecular Medicine, |
RCV000156783 | SCV000206504 | likely pathogenic | Arrhythmogenic right ventricular cardiomyopathy | 2014-08-22 | criteria provided, single submitter | clinical testing | The Thr974fs variant in DSP has not been previously reported in individuals with cardiomyopathy. Data from large population studies is insufficient to assess th e frequency of this variant. This variant is predicted to cause a frameshift, wh ich alters the protein?s amino acid sequence beginning at position 974 and lead to a premature termination codon 3 amino acids downstream. This alteration is th en predicted to lead to a truncated or absent protein. Frameshift and nonsense v ariants in DSP have been reported in patients with ARVC (http://arvcdatabase.inf o/), but recent evidence supports that they can also cause DCM (Pugh 2014). In s ummary, although additional studies are required to fully establish its clinical significance, the Thr974fs variant is likely pathogenic. |