Total submissions: 6
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001849966 | SCV002258902 | likely benign | Arrhythmogenic cardiomyopathy with wooly hair and keratoderma; Arrhythmogenic right ventricular dysplasia 8 | 2024-11-07 | criteria provided, single submitter | clinical testing | |
Fulgent Genetics, |
RCV002498653 | SCV002790288 | uncertain significance | Arrhythmogenic cardiomyopathy with wooly hair and keratoderma; Arrhythmogenic right ventricular dysplasia 8; Lethal acantholytic epidermolysis bullosa; Woolly hair-skin fragility syndrome; Keratosis palmoplantaris striata 2; Cardiomyopathy, dilated, with wooly hair, keratoderma, and tooth agenesis | 2021-09-10 | criteria provided, single submitter | clinical testing | |
Color Diagnostics, |
RCV003531968 | SCV004363265 | uncertain significance | Cardiomyopathy | 2024-03-07 | criteria provided, single submitter | clinical testing | This missense variant replaces arginine with glutamine at codon 150 of the DSP protein. Computational prediction suggests that this variant may not impact protein structure and function (internally defined REVEL score threshold <= 0.5, PMID: 27666373). To our knowledge, functional studies have not been reported for this variant. This variant has not been reported in individuals affected with cardiovascular disorders in the literature. This variant has been identified in 9/282198 chromosomes in the general population by the Genome Aggregation Database (gnomAD). The available evidence is insufficient to determine the role of this variant in disease conclusively. Therefore, this variant is classified as a Variant of Uncertain Significance. |
All of Us Research Program, |
RCV003998154 | SCV004828633 | uncertain significance | Arrhythmogenic cardiomyopathy with wooly hair and keratoderma | 2023-09-17 | criteria provided, single submitter | clinical testing | This missense variant replaces arginine with glutamine at codon 150 of the DSP protein. Computational prediction suggests that this variant may not impact protein structure and function (internally defined REVEL score threshold <= 0.5, PMID: 27666373). To our knowledge, functional studies have not been reported for this variant. This variant has not been reported in individuals affected with cardiovascular disorders in the literature. This variant has been identified in 9/282198 chromosomes in the general population by the Genome Aggregation Database (gnomAD). The available evidence is insufficient to determine the role of this variant in disease conclusively. Therefore, this variant is classified as a Variant of Uncertain Significance. |
Ambry Genetics | RCV004992013 | SCV005570922 | uncertain significance | Cardiovascular phenotype | 2024-11-29 | criteria provided, single submitter | clinical testing | The c.449G>A (p.R150Q) alteration is located in exon 4 (coding exon 4) of the DSP gene. This alteration results from a G to A substitution at nucleotide position 449, causing the arginine (R) at amino acid position 150 to be replaced by a glutamine (Q). Based on insufficient or conflicting evidence, the clinical significance of this alteration remains unclear. |
Blueprint Genetics | RCV000143883 | SCV000188752 | uncertain significance | Collapse (finding) | 2013-11-08 | no assertion criteria provided | clinical testing |