Total submissions: 5
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Gene |
RCV000181260 | SCV000233543 | uncertain significance | not provided | 2018-05-30 | criteria provided, single submitter | clinical testing | The Q1648R variant has been previously reported in four Chinese individuals with ARVC (Bao et al., 2013), and it has been observed in other individuals referred for cardiomyopathy genetic testing at GeneDx. However, the individuals at GeneDx also harbored variants in other genes, and thus far, no informative segregation data are available for the published cases or the cases observed at GeneDx. Additionally, this variant has been collectively identified in 3/1454 (0.21%) alleles from ostensibly healthy individuals (Kapplinger et al., 2011; Bao et al., 2013), and has been observed in 50/18852 (0.27%) alleles from individuals of East Asian ancestry in large population cohorts (Lek et al., 2016). Furthermore, in-silico analyses, including protein predictors and evolutionary conservation, support that this variant does not alter protein structure/function. Nevertheless, Q1648R is a semi-conservative amino acid substitution, which may impact secondary protein structure as these residues differ in some properties. |
Color Diagnostics, |
RCV000778027 | SCV000914139 | likely benign | Cardiomyopathy | 2018-10-03 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV001087060 | SCV001007731 | likely benign | Arrhythmogenic cardiomyopathy with wooly hair and keratoderma; Arrhythmogenic right ventricular dysplasia 8 | 2025-01-27 | criteria provided, single submitter | clinical testing | |
Ambry Genetics | RCV002336443 | SCV002643900 | likely benign | Cardiovascular phenotype | 2019-10-04 | criteria provided, single submitter | clinical testing | This alteration is classified as likely benign based on a combination of the following: seen in unaffected individuals, population frequency, intact protein function, lack of segregation with disease, co-occurrence, RNA analysis, in silico models, amino acid conservation, lack of disease association in case-control studies, and/or the mechanism of disease or impacted region is inconsistent with a known cause of pathogenicity. |
All of Us Research Program, |
RCV003996634 | SCV004815001 | likely benign | Arrhythmogenic cardiomyopathy with wooly hair and keratoderma | 2024-08-30 | criteria provided, single submitter | clinical testing |