Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Seattle Children's Hospital Molecular Genetics Laboratory, |
RCV002254420 | SCV002525568 | pathogenic | Capillary malformation-arteriovenous malformation syndrome | 2022-01-31 | criteria provided, single submitter | clinical testing | The p.Gln41* variant has not been observed in large population studies (Genome Aggregation Database v2.1.1). To our knowledge, this variant has also not been reported in the medical literature or patient-specific databases. While this specific nonsense variant has not been previously reported as pathogenic, other loss-of-function variants affecting EPHB4 have been reported in CM-AVM2 (MIM #618196) (NBK52764, PMID: 28687708). |