Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
SIB Swiss Institute of Bioinformatics | RCV000852307 | SCV000994940 | uncertain significance | Capillary malformation-arteriovenous malformation 2 | 2019-03-29 | criteria provided, single submitter | curation | This variant is interpreted as Uncertain significance for Capillary malformation-arteriovenous malformation 2. The following ACMG Tag(s) were applied: PM2-Supporting: Absent from controls (or at extremely low frequency if recessive) in Exome Sequencing Project, 1000 Genomes Project, or Exome Aggregation Consortium. PM1: Located in a mutational hot spot and/or critical and well-established functional domain (e.g.,active site of an enzyme) without benign variation. PP3: Multiple lines of computational evidence support a deleterious effect on the gene or gene product. |
Seattle Children's Hospital Molecular Genetics Laboratory, |
RCV002254320 | SCV002525682 | likely pathogenic | not provided | 2021-09-10 | criteria provided, single submitter | clinical testing | This variant has previously been reported in an individual with a capillary malformation (PMID: 28687708). This is an ultra-rare variant in large population studies (observed in 1 of 251,032 alleles, gnomAD v2.1.1.). |