Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Ambry Genetics | RCV000623700 | SCV000742723 | likely pathogenic | Inborn genetic diseases | 2017-08-16 | criteria provided, single submitter | clinical testing | |
Genomic Medicine Center of Excellence, |
RCV001798931 | SCV004806417 | likely pathogenic | Coffin-Lowry syndrome | 2024-03-25 | criteria provided, single submitter | clinical testing | |
Gene |
RCV004702205 | SCV005201196 | pathogenic | not provided | 2023-12-18 | criteria provided, single submitter | clinical testing | Reported in the literature in a patient with features of RPS6KA3-Related Coffin-Lowry Spectrum Disorder and functional studies demonstrate that this non-canonical splice site variant resulted in loss-of-function (PMID:11992250); Not observed at significant frequency in large population cohorts (gnomAD); This variant is associated with the following publications: (PMID: 11992250) |
OMIM | RCV001798931 | SCV000032662 | pathogenic | Coffin-Lowry syndrome | 2002-06-01 | no assertion criteria provided | literature only |