Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Laboratory of Cell Biology, |
RCV000785881 | SCV000902258 | likely pathogenic | Dynein arm defect of respiratory motile cilia; Absent inner and outer dynein arms; Abnormal ciliary motility; Bronchiectasis | criteria provided, single submitter | clinical testing | The variant detected in a patient with kartagner syndrome lacking both dynein arms in its axoneme. This is a synonymous variant that is predicted to affect splicing and reduced mRNA expression were observed in the patient's cells. |