Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001318486 | SCV001509188 | uncertain significance | Hypoplastic left heart syndrome | 2023-05-01 | criteria provided, single submitter | clinical testing | In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. An algorithm developed to predict the effect of missense changes on protein structure and function (PolyPhen-2) suggests that this variant is likely to be disruptive. ClinVar contains an entry for this variant (Variation ID: 1019101). This variant has not been reported in the literature in individuals affected with HAND1-related conditions. This variant is present in population databases (rs764242373, gnomAD 0.04%), and has an allele count higher than expected for a pathogenic variant. This sequence change replaces tyrosine, which is neutral and polar, with cysteine, which is neutral and slightly polar, at codon 72 of the HAND1 protein (p.Tyr72Cys). |
Ambry Genetics | RCV004034938 | SCV004065036 | uncertain significance | not specified | 2023-08-15 | criteria provided, single submitter | clinical testing | The c.215A>G (p.Y72C) alteration is located in exon 1 (coding exon 1) of the HAND1 gene. This alteration results from a A to G substitution at nucleotide position 215, causing the tyrosine (Y) at amino acid position 72 to be replaced by a cysteine (C). Based on insufficient or conflicting evidence, the clinical significance of this alteration remains unclear. |