Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
3billion | RCV005252165 | SCV005904064 | uncertain significance | Developmental and epileptic encephalopathy, 26 | 2023-10-25 | criteria provided, single submitter | clinical testing | The variant is not observed in the gnomAD v2.1.1 dataset. Predicted Consequence/Location: Missense changes are a common disease-causing mechanism. In silico tool predictions suggest damaging effect of the variant on gene or gene product [REVEL: 0.92 (>=0.6, sensitivity 0.68 and specificity 0.92); 3Cnet: 0.98 (>=0.6, sensitivity 0.72 and precision 0.9)]. Different missense changes at the same codon (p.Ser202Cys, p.Ser202Phe) have been reported to be associated with KCNB1-related disorder (ClinVar ID: VCV000932381 /PMID: 28806457). Therefore, this variant is classified as Likely pathogenic according to the recommendation of ACMG/AMP guideline. |