Total submissions: 5
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Gene |
RCV000490061 | SCV000577411 | uncertain significance | not provided | 2017-03-30 | criteria provided, single submitter | clinical testing | A variant of uncertain significance has been identified in the KIF5A gene. The P935S variant has not been published as a pathogenic variant, nor has it been reported as a benign variant to our knowledge. The P935S variant is not observed at a significant frequency in large population cohorts (Lek et al., 2016; 1000 Genomes Consortium et al., 2015; Exome Variant Server). The P935S variant is a non-conservative amino acid substitution, which is likely to impact secondary protein structure as these residues differ in polarity, charge, size and/or other properties. This substitution occurs at a position that is conserved in mammals. However, in silico analysis is inconsistent in its predictions as to whether or not the variant is damaging to the protein structure/function. Therefore, based on the currently available information, it is unclear whether this variant is a pathogenic variant or a rare benign variant. |
Ce |
RCV000490061 | SCV001748373 | uncertain significance | not provided | 2022-05-01 | criteria provided, single submitter | clinical testing | KIF5A: PM2, BP4 |
Institute for Clinical Genetics, |
RCV000490061 | SCV002009749 | uncertain significance | not provided | 2021-11-03 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV002526034 | SCV003253024 | likely benign | Spastic paraplegia | 2024-10-15 | criteria provided, single submitter | clinical testing | |
Prevention |
RCV004737559 | SCV005352095 | uncertain significance | KIF5A-related disorder | 2024-06-10 | no assertion criteria provided | clinical testing | The KIF5A c.2803C>T variant is predicted to result in the amino acid substitution p.Pro935Ser. To our knowledge, this variant has not been reported in the literature. This variant is reported in 0.0035% of alleles in individuals of European (Non-Finnish) descent in gnomAD. At this time, the clinical significance of this variant is uncertain due to the absence of conclusive functional and genetic evidence. |