Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV002932485 | SCV003260338 | likely pathogenic | not provided | 2024-02-16 | criteria provided, single submitter | clinical testing | This sequence change replaces valine, which is neutral and non-polar, with aspartic acid, which is acidic and polar, at codon 477 of the SLC27A4 protein (p.Val477Asp). This variant is present in population databases (rs147688821, gnomAD 0.006%). This missense change has been observed in individuals with ichthyosis prematurity syndrome (PMID: 21450060, 24889544). It has also been observed to segregate with disease in related individuals. ClinVar contains an entry for this variant (Variation ID: 2052115). Advanced modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) performed at Invitae indicates that this missense variant is expected to disrupt SLC27A4 protein function with a positive predictive value of 80%. In summary, the currently available evidence indicates that the variant is pathogenic, but additional data are needed to prove that conclusively. Therefore, this variant has been classified as Likely Pathogenic. |
Fulgent Genetics, |
RCV005050657 | SCV005679937 | likely pathogenic | Ichthyosis prematurity syndrome | 2024-05-08 | criteria provided, single submitter | clinical testing |