Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV003079037 | SCV003460736 | pathogenic | Autoimmune lymphoproliferative syndrome due to CTLA4 haploinsufficiency | 2022-03-28 | criteria provided, single submitter | clinical testing | This sequence change creates a premature translational stop signal (p.Trp165*) in the CTLA4 gene. It is expected to result in an absent or disrupted protein product. Loss-of-function variants in CTLA4 are known to be pathogenic (PMID: 25213377, 25329329). This variant is not present in population databases (gnomAD no frequency). This premature translational stop signal has been observed in individual(s) with CTLA4 haploinsufficiency (PMID: 28960754, 30048690). For these reasons, this variant has been classified as Pathogenic. |