Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Suna and Inan Kirac Foundation Neurodegeneration Research Laboratory, |
RCV001095485 | SCV001251079 | benign | Amyotrophic lateral sclerosis | 2020-03-31 | criteria provided, single submitter | research | |
Labcorp Genetics |
RCV002554875 | SCV003269303 | uncertain significance | not provided | 2024-10-14 | criteria provided, single submitter | clinical testing | This sequence change replaces arginine, which is basic and polar, with histidine, which is basic and polar, at codon 103 of the ERBB4 protein (p.Arg103His). This variant is present in population databases (rs754487821, gnomAD 0.009%). This missense change has been observed in individual(s) with amyotrophic lateral sclerosis (ALS) (PMID: 29895397). ClinVar contains an entry for this variant (Variation ID: 873273). Invitae Evidence Modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) indicates that this missense variant is not expected to disrupt ERBB4 protein function with a negative predictive value of 80%. In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
Prevention |
RCV003396744 | SCV004104108 | uncertain significance | ERBB4-related disorder | 2024-01-22 | no assertion criteria provided | clinical testing | The ERBB4 c.308G>A variant is predicted to result in the amino acid substitution p.Arg103His. This variant was reported in two individuals with amyotrophic lateral sclerosis (ALS); however, one of the individuals also carried a pathogenic variant in an ALS-associated gene providing the diagnosis (Table 1, Narain et al. 2018. PubMed ID: 29895397; eTable 1 and eTable 2A, Grassano et al. 2022. PubMed ID: 35896380). This variant is reported in 0.0093% of alleles in individuals of European (Non-Finnish) descent in gnomAD. Although we suspect that this variant may be benign, at this time, the clinical significance of this variant is uncertain due to the absence of conclusive functional and genetic evidence. |