Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Baylor Genetics | RCV000679993 | SCV000807430 | pathogenic | Congenital cataract-progressive muscular hypotonia-hearing loss-developmental delay syndrome | 2017-09-01 | criteria provided, single submitter | clinical testing | This frameshift mutation is categorized as deleterious according to ACMG guidelines (PMID:18414213) and was found once in our laboratory in trans with a pathogenic variant in a 13-year-old male with profound delays, tremulousness, respiratory distress, congenital ataracts, hypoglycemia, lactic acidemia, autistic features, scoliosis, pica, hypotonia, intermittent alopecia, osteoporosis, episodes of hypophosphatemia. Similarly affected sister had same compound heterozygous genotype. |
Mayo Clinic Laboratories, |
RCV000676337 | SCV000802109 | likely pathogenic | not provided | 2016-03-08 | no assertion criteria provided | clinical testing | |
OMIM | RCV000679993 | SCV001430678 | pathogenic | Congenital cataract-progressive muscular hypotonia-hearing loss-developmental delay syndrome | 2020-08-20 | no assertion criteria provided | literature only |