Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Gene |
RCV003319681 | SCV004023599 | pathogenic | not provided | 2023-02-01 | criteria provided, single submitter | clinical testing | In silico analysis supports that this missense variant has a deleterious effect on protein structure/function; Not observed at significant frequency in large population cohorts (gnomAD); This variant is associated with the following publications: (PMID: 33240976, 35531093) |
Dept. |
RCV004593262 | SCV005081866 | likely pathogenic | Cataract 1 multiple types | 2023-01-21 | criteria provided, single submitter | curation | Variant identified and curated during a GJA8 specific review of the literature in relation to pediatric or congenital cataract. ACMG-AMP criteria applied: PP1(Strong), PM1(Supporting), PM2(Supporting), PP3. Original variant report: PMID:33240976. The cataract phenotype reported for this variant is: Y-shaped nuclear. Additional phenotype/s reported in these individual/s are: Strabismus, amblyopia. Gene review and curation guidelines are outlined in: https://doi.org/10.1080/17469899.2023.2160320 |